At-Home Telespirometry [AHT] in Amyotrophic Lateral Sclerosis [ALS]
Eufrosina Young1, Jenny Meyer1, Dongliang Wang2, Bhavya Narapureddy1, Birendra Sah3, Dragos Manta3, Urvi Desai4, Benjamin Brooks5
1Neurology, 2Biostatistics, 3Pulmonary, Upstate University Hospital, 4Neurology, Atrium Health, 5Neurology, Clinical Trials Planning LLC
Objective:

We measured erect seated FVC [eFVC] and supine FVC [sFVC] using in-clinic-conventional [Viaire and Vyasis, USA], in-clinic-portable and at-home-portable [MIR Spirobank Smart, Italy] spirometers with in-person and internet-based respiratory therapist coaching.

We adapted baseline eFVC in an algorithm to facilitate prognostication of individual patients and customize management strategies as described for lung transplantation patients [Mohanka 2000] and ALS [Elamin 2018, Torrieri 2022].
Background:

Classification of disease progression based on stratified forced vital capacity is a model used to identify clinical phenotypes in ALS [Ackrivo 2019]. Remote monitoring of FVC using internet-based system is a validated method in primary pulmonary disorders, but not in ALS.

Design/Methods:

Electronic health records of 22/95 ALS clinic patients (23%) from single ALS center that launched AHT between July 2020 to June 2021 was reviewed in this IRB-approved retrospective study. Patients were stratified according to baseline eFVC >=80 %, 60%-80%, <=60% predicted.

Results:

eFVC acquired within a 7-day period (N=16) were highly correlated in liters [R2=0.926; p<0.0001] and %p [R2=0.922, p < 0.001]. Bland-Altman analysis showed a mean difference of 0.15L [conventional – portable]; 95% limits of agreement =-0.40L to 0.70L; 2.7 %p [-12.1% to 17.5%].

eFVC < 60 %p at baseline entry had statistically significant [ < 60 %p mean = 766 days, 95%CI= 368 to 1162 days; > 60 %p mean = 2638 days, 95%CI = 1479 to 3797 days; HR = 0.2218 95% CI = 0.07614 to 0.8008; P = 0.0215] decreased survival compared with the upper tertiles combined.  
Conclusions:

We are conducting a larger prospective confirmatory study [NCT05106569] to validate AHT measurement of SVC [slow vital capacity] to determine if a higher level of peak lung functions at ALS diagnosis would be associated with longer survival and better outcomes in relation to overall respiratory care management.

10.1212/WNL.0000000000204029